Robinson, LiamSengoatsi, TshepangVan Heerden, Willem Francois Petrus2022-09-012022-09-012021-03Robinson, L., Sengoatsi, T. & van Heerden, W.F.P. Concomitant Congenital Intraoral Dermoid Cyst and Heterotopic Gastrointestinal Cyst. Head and Neck Pathology 15, 298–302 (2021). https://doi.org/10.1007/s12105-020-01160-0.1936-055X (print)1936-0568 (online)10.1007/s12105-020-01160-0https://repository.up.ac.za/handle/2263/87018Sublingual dermoid cysts and oral heterotopic gastrointestinal cysts are well-documented causes of sublingual swellings in infants. However, the simultaneous occurrence of both cysts is an extremely rare phenomenon, with only two previous cases reported in literature. We present a case of 1-month-old neonate with a cystic ventral tongue mass that on histologic examination showed a dermoid cyst with co-existing heterotopic gastric-type epithelium in the wall. Additional histochemical stains revealed focal areas of colonic metaplasia within the heterotopic gastric epithelium. CDX2 immunohistochemical staining confirmed derivation from colonic epithelium.en© Springer Science+Business Media, LLC, part of Springer Nature 2020. The original publication is available at : https://link.springer.com/journal/12105.Congenital sublingual cystSublingual dermoid cystOral heterotopic gastrointestinal cystNeonateSublingual swellingDermoid cystHeterotopic gastrointestinal cystCystic ventral tongue massHistologic examinationGastric-type epitheliumColonic metaplasiaCDX2 immunohistochemical stainingPediatric oral pathologyRare oral conditionsHealth sciences articles SDG-03SDG-03: Good health and well-beingHealth sciences articles SDG-10SDG-10: Reduced inequalitiesHealth sciences articles SDG-17SDG-17: Partnerships for the goalsPostprint Article